J Korean Assoc Oral Maxillofac Surg 2017; 43(3): 171~177
Amniotic constriction band: a report of two cases with unique clinical presentations
Sunil Richardson1, Rakshit Vijay Khandeparker1, Philippe Pellerin2
1Richardsons Dental and Craniofacial Hospital, Nagercoil, India, 2Department of National Reference, Center for Rare Craniomaxillofacial Malformations, Centre Hospitalier Régional Universitaire de Lille, Lille, France
Sunil Richardson
Richardsons Dental and Craniofacial Hospital, #71 Trivandrum Highway, Chunkan Kadai, Parvathipuram, Nagercoil, Kanyakumari, Tamil Nadu 629003, India
TEL: +91-9944428056 E-mail: sunilrichardson145@gmail.com ORCID: http://orcid.org/0000-0002-2141-9201
Received March 29, 2016; Revised June 12, 2016; Accepted July 6, 2016.; Published online June 30, 2017.
© Korean Association of Oral and Maxillofacial Surgeons. All rights reserved.

This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.
 Abstract
Amniotic constriction band is a rare clinical entity with varied manifestations that range from a combination of congenital malformations to isolated malformations that are unique to each patient. The etiology of this entity remains unknown. Herein, we highlight two cases of amniotic constriction band that presented to our unit with unique clinical characteristics. To the best of our knowledge, an isolated circumferential band of scarring on the face with ocular involvement, as demonstrated by the first case, and a combination of bilateral complete cleft lip and palate with bilateral microphthalmia, auto-amputation of the right thumb, and a constriction band on the left thumb, as demonstrated by the second case, are extremely rare presentations of amniotic constriction band that were not previously reported in the literature and therefore necessitate a special mention. We discuss potential etiologies for these cases and review the existing literature on this entity.
Keywords: Amniotic constriction band, Circumferential band, Bilateral cleft lip and palate, Auto-amputation, Microphthalmos


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30 June 2017
Vol. 43
No. 3 pp. 145~212

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